Submission Details

Submitter:

Classification:
Moderate
GENCC:100003
Gene:
Disease:
MGAT2-congenital disorder of glycosylation
Mode Of Inheritance:
Autosomal recessive
Evaluated Date:
11/07/2024
Evidence/Notes:

MGAT2 was first reported in relation to MGAT2-congenital disorder of glycosylation in 1996 (Tan et al., PMID: 8808595). Seven unique variants (missense, nonsense, and frameshift) that have been reported in seven probands in six publications are included in this curation. This gene-disease relationship is also supported by two mouse models – a full gene knockout (Wang et al., PMID: 11805078, Wang et al., PMID:12417412) and a targeted knockout (Ryan et al., PMID: 24310166). In summary, there is moderate evidence to support this gene-disease relationship. While more evidence is needed to establish this relationship definitively, no convincing contradictory evidence has emerged. Of the few reports of prenatally diagnosed MGAT2-CDG, hydrops fetalis has been described in one case (PMID: 28742265) and a single case of preterm birth (PMID: 33044030) was separately reported. There is insufficient evidence to establish causation of a prenatal phenotype. This classification was approved by the ClinGen Congenital Disorders of Glycosylation GCEP on the meeting date November 7, 2024 (SOP Version 11).

MGAT2 was first reported in relation to MGAT2-congenital disorder of glycosylation in 1996 (Tan et al., PMID: 8808595). Seven unique variants (missense, nonsense, and frameshift) that have been reported in seven probands in six publications are included in this curation. This gene-disease relationship is also supported by two mouse models – a full gene knockout (Wang et al.,PMID: 11805078, Wang et al., PMID:12417412) and a targeted knockout (Ryan et al., PMID: 24310166). In summary, there is moderate evidence to support this gene-disease relationship. While more evidence is needed to establish this relationship definitively, no convincing contradictory evidence has emerged. This classification was approved by the ClinGen Congenital Disorders of Glycosylation GCEP on the meeting date November 7, 2024 (SOP Version 11).

PubMed IDs:
8808595 11228641 11805078 12417412 22105986 24310166 28742265 33044030 33960646
Public Report:
Assertion Criteria:
Submitter Submitted Date:
12/05/2025

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